An Unusual Case of Recurrent Pyocolpos Following Midtrimester Miscarriage Revealed as Obstructed Hemivagina with Ipsilateral Renal Agenesis (OHVIRA) Syndrome
Main Article Content
Abstract
Obstructed hemivagina with ipsilateral renal agenesis (OHVIRA Syndrome) is a rare congenital anomaly. It mostly presents with severe dysmenorrhea and a palpable mass due to unilateral hematocolpos. Sometime it presents in unusual way with prolonged vaginal bleeding and profuse vaginal discharge. We report a case of an 18-year-old married female with OHVIRA syndrome presenting late with symptoms of recurrent pyocolpos following dilatation and evacuation for midtrimester miscarriage that was diagnosed on the basis of MRI and managed by vaginal septotomy.
Downloads
Article Details
Copyright (c) 2014 Haldar M, et al.

This work is licensed under a Creative Commons Attribution 4.0 International License.
Ashton D, Amin HK, Richart RM, Neuwirth RS (1988) The incidence of asymptomatic uterine anomalies in women undergoing transcervical tubal sterilization. Obstet Gynecol 72: 28-30.
Kimble RM, Khoo SK, Baartz D, Kimble RM (2009) The obstructed hemivagina, ipsilateral renal anomaly, uterus didelphys triad. Aust NZ J Obstet Gynaecol 49: 554-557. DOI: https://doi.org/10.1111/j.1479-828X.2009.01063.x
Moore KL, Persaud TVN (2003) The urogenital system: the developmental of the genital system. In: The developing human: clinically oriented embryology, 7th edn. WB Saunders, Philadelphia.
Mijsberg WA (1924) Uber die entwicklung der vagina, des hymen und des sinus urogenitalis beim menschen. Z Anat Entwicklungsgesch 74: 684-760. DOI: https://doi.org/10.1007/BF02117083
Acien P (1992) Embryological observations on the female genital tract. Hum Reprod 7: 437-445. DOI: https://doi.org/10.1093/oxfordjournals.humrep.a137666
Christianson MS, Yates MM, Woo I, Khafagy A, Garcia JE, et al. (2012) Obstructed hemivagina and ipsilateral renal anomaly (OHVIRA): diagnostic features and managementof a frequently misdiagnosed syndrome. Fertil Steril 98: S222. DOI: https://doi.org/10.1016/j.fertnstert.2012.07.806
Marjan Attaran. Surgical techniques for management of anomalies of the Mullerian ducts. In: Tommase Falcone, William W.Hurd, editors. Clinical reproductive medicine and surgery: a practical guide. 2nd edition. New York: Springer Science+Business Media; 2013. DOI: https://doi.org/10.1007/978-1-4614-6837-0_21
Dhar H, Yasser AR, Illham H (2011) Uterusdidelphys with obstructed hemi vagina, ipsilateral renal agenesis and right pyocolpos: A case report. Oman Med J 26: 447-450. DOI: https://doi.org/10.5001/omj.2011.114
Troiano RN, McCarthy SM (2004) Mullerian duct anomalies: imaging and clinical issues. State of the art. Radiology 233:19-34. DOI: https://doi.org/10.1148/radiol.2331020777
Stassart JP, Nagel TC, Prem KA, Phipps WR (1992) Uterus didelphys, obstructed hemivagina, and ipsilateral renal agenesis: the University of Minnesota experience. Fertil Steril 57: 756-761. DOI: https://doi.org/10.1016/S0015-0282(16)54955-3
Scarsbrook AF, Moore NR (2003) MRI appearance of Mullerian duct abnormalities. Clin Radiol 58: 747-754. DOI: https://doi.org/10.1016/S0009-9260(03)00212-5
Gholoum S, Puligandla PS, Hui T, et al. (2006) Management and outcome of patients with combined vaginal septum, bifid uterus and ipsilateral renal agenesis (Herlyn-Werner-Wunderlich syndrome). J Pediatr Surg 41: 987-992. DOI: https://doi.org/10.1016/j.jpedsurg.2006.01.021